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Intrathecal baclofen for severe torsion dystonia in a child
Author(s) -
Paret G,
Tirosh R,
Zeev B Ben,
Vardi A,
Brandt N,
Barzilay Z
Publication year - 1996
Publication title -
acta pædiatrica
Language(s) - English
Resource type - Journals
SCImago Journal Rank - 0.772
H-Index - 115
eISSN - 1651-2227
pISSN - 0803-5253
DOI - 10.1111/j.1651-2227.1996.tb14109.x
Subject(s) - medicine , dystonia , baclofen , intrathecal , anesthesia , conservative treatment , surgery , psychiatry , receptor , agonist
The successful use of intrathecal baclofen, a structural analogue of γ‐aminobutyric acid, is described in the treatment of a 9‐year‐old boy with intractable torsion dystonia, not responding to conservative treatment. To our knowledge, this is the first reported case of continuous intrathecal baclofen for hereditary torsion dystonia. This case suggests that a continuous intrathecal infusion of baclofen may facilitate remission of intractable torsion dystonia, and provides a basis for further investigation of the treatment of intractable childhood dystonia.