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The quality of life in genetic neuromuscular disease questionnaire: Rasch validation of the French version
Author(s) -
Dany Antoine,
Rapin Amandine,
Lavrard Brice,
Saoût Virginie,
Réveillère Christian,
Bassez Guillaume,
Tiffreau Vincent,
Péréon Yann,
Sacconi Sabrina,
Eymard Bruno,
Dramé Moustapha,
Jolly Damien,
Novella JeanLuc,
Hardouin JeanBenoit,
Boyer François C.
Publication year - 2017
Publication title -
muscle and nerve
Language(s) - English
Resource type - Journals
SCImago Journal Rank - 1.025
H-Index - 145
eISSN - 1097-4598
pISSN - 0148-639X
DOI - 10.1002/mus.25598
Subject(s) - rasch model , intraclass correlation , quality of life (healthcare) , concurrent validity , reliability (semiconductor) , neuromuscular disease , psychometrics , physical therapy , physical medicine and rehabilitation , medicine , psychology , internal consistency , disease , clinical psychology , developmental psychology , power (physics) , physics , nursing , quantum mechanics
Slowly progressive, genetic neuromuscular diseases (gNMDs) often lead to important motor deficiencies and functional limitations. The Quality of Life in Genetic Neuromuscular Disease Questionnaire (QoL‐gNMD) is a new health‐related quality‐of‐life questionnaire developed for these patients. The purpose of the present study was to validate the French version of the QoL‐gNMD and to calibrate its measurement system. Methods Both the QoL‐gNMD and a validated generic questionnaire (WHOQOL‐BREF) were administered to patients. Validation was performed using item response theory. The partial credit model (Rasch) was used to calibrate each domain. Results Three hundred fifteen adult patients were included. All 3 domains showed adequate psychometric properties (internal consistency: person separation index >0.77; repeatability: test–retest intraclass correlation coefficient >0.75, scalability coefficient >0.38) and fitted the partial credit model. The QoL‐gNMD also demonstrated adequate concurrent validity with the WHOQOL‐BREF. Discussion The QoL‐gNMD showed adequate psychometric properties and can be used in clinical settings. Although not anchor‐based, the minimum detectable change tables help in interpreting score change. Muscle Nerve 56 : 1085–1091, 2017