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Laryngeal stenosis in a patient with severe congenital neutropenia
Author(s) -
Bando Hideki,
Nagao Hikaru,
Nishio Takeshi,
Hirota Ryuichi,
Sakaguchi Hirofumi,
Imamura Toshihiko,
Hisa Yasuo
Publication year - 2013
Publication title -
the laryngoscope
Language(s) - English
Resource type - Journals
SCImago Journal Rank - 1.181
H-Index - 148
eISSN - 1531-4995
pISSN - 0023-852X
DOI - 10.1002/lary.23375
Subject(s) - medicine , tracheotomy , congenital neutropenia , laryngoscopy , granuloma , surgery , neutropenia , airway , lesion , tracheal stenosis , stenosis , stoma (medicine) , bronchoscopy , anesthesia , radiology , intubation , pathology , chemotherapy
Objectives/Hypothesis: We report the first case of laryngeal stenosis with granuloma in a patient with severe congenital neutropenia (SCN). Study Design: Case report and retrospective review. Methods: Review of medical records. Results: A 6‐year‐old female who was diagnosed with SCN presented with a cough and wheezing. An endoscopic study revealed laryngeal stenosis with granuloma. Tracheotomy and direct laryngoscopy were performed under general anesthesia, and administration of granulocyte colony‐stimulating factor was started. The laryngeal granuloma disappeared 3 weeks later, and the tracheal stoma was closed. Conclusions: Presence of a laryngeal lesion should be considered in SCN patients with persistent airway symptoms.