
Surgical treatment of gastrointestinal hereditary hemorrhagic telangiectasia
Author(s) -
Yen MinHsuan,
Chen ChiungNien
Publication year - 2016
Publication title -
acute medicine and surgery
Language(s) - English
Resource type - Journals
ISSN - 2052-8817
DOI - 10.1002/ams2.158
Subject(s) - telangiectasia , medicine , dermatology , surgery
Case A 48‐year‐old man with a history of gastrointestinal bleeding from O sler– W eber– R endu disease presented with recurrent hematemesis and tarry stool. He received repeated endoscopic therapy, but profound component therapy was still needed. Because repeated gastrointestinal bleeding was caused by same bleeder, tattoo‐assisted laparoscopic gastric wedge resection was carried out. Outcome The pathology showed vascular abnormalities that involved gastric mucosal and submucosal layers. After surgery, the blood transfusion for the patient is not seen.Conclusion Osler–Weber–Rendu is a hereditary disease characterized by vascular abnormalities of the nose, skin, lung, brain, and gastrointestinal tract. Management of gastrointestinal bleeding requires medical treatment first, and there are rare reports of surgical treatment. Our pathology findings showed a transmucosal vessel lesion, which had poor response to endoscopic treatment. Surgical intervention may be considered in the patient with gastrointestinal bleeding refractory to endoscopic therapy.